Gyawali, Bigyan RDutta, HeempaliTripathi, Prashant2026-04-062026-04-062019https://hdl.handle.net/20.500.14572/5687Bigyan R Gyawali, Heempali Dutta, Prashant Tripathi Department of Otorhinolaryngology and Head and Neck Surgery, Maharajgunj Medical Campus, Ganesh Man Singh Memorial Academy of ENT - Head & Neck Studies, Tribhuvan University Teaching Hospital, Kathmandu, NepalABSTRACT Thyroglossal duct anomaly is one of the commonest congenital anomalies with midline neck manifestation. Though commonest location mentioned in the literature is thyrohyoid, several rare presentations have also been described. Here, we present a very rare case of thyroglossal fistula manifesting in submental region. Keywords:Fistula, submental, thyroglossal ducten-USFistulasubmentalthyroglossal ductThyroglossal Duct Fistula with an Unusual Presentation: A Case ReportArticle