Publication:
ARID1A-Associated Coffin-Siris Syndrome: A Rare Case Report with Steroid-Resistant Nephrotic Syndrome and Single Kidney

Date

2024

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Perinatal Society of Nepal (PESON)

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Abstract

Abstract: Coffin-Siris syndrome (CSS), a rare BAFopathy, is characterized by developmental delay, dysmorphic features, and variable anomalies. We report a 12-year-old boy with a novel ARID1A truncating mutation presenting with global developmental delay, facial dysmorphism, single kidney, and steroid-resistant nephrotic syndrome (SRNS). Genetic analysis confirmed a heterozygous p.Glu1017Ter mutation in ARID1A. This report expands the phenotypic spectrum of CSS by highlighting its association with glomerular disease, a previously unreported feature.

Description

Md Habibullah Sk Neonatologist, DM Neonatology, Senior Resident, Department of Neonatology, Institute of Post Graduate Medical Education & Research and SSKM Hospital, 244, A J C Bose Road, Kolkata-700020, India Mohsina Naj Paediatrician, Post Doctoral Trainee, Department of Nephrology, Institute of Post Graduate Medical Education & Research and SSKM Hospital, 244, A J C Bose Road, Kolkata-700020, India

Keywords

Coffin-Siris syndrome, ARID1A, Steroid-resistant nephrotic syndrome, Single kidney, Developmental delay

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