Publication:
An Early Presentation of a Genomic Variant of Mucopolysaccharidoses II in a Female Newborn Baby

creativeworkseries.issnISSN 1990-7974 eISSN 1990-7982
dc.contributor.authorRitesh
dc.contributor.authorSingh, Harsh Mohinder
dc.date.accessioned2026-01-09T08:08:11Z
dc.date.available2026-01-09T08:08:11Z
dc.date.issued2018
dc.descriptionRitesh Department of Paediatrics, ITFH Tajikistan Harsh Mohinder Singh Base Hospital Barrackpore, North Parganas, West Bengal, India
dc.description.abstractAbstract: Mucopolysaccharidoses II is a X-linked genetic disorder caused by the deficiency of lysosomal enzyme Iduronate sulfate sulfatase due to mutations of Iduronate 2-sulfatase (IDS) gene which results in accumulation of intralysosomal glycosaminoglycan. X inactivation and gene alterations are known to cause this entity in a female child. We report an unusual case of missense mutation of IDS gene in heterozygous variant with dominant expression in a female neonate presented in early newborn period with incurable severity. X- linked recessive (heterozygous) missense mutation of Exon 8 in IDS gene confirmed a case of Mucopolysaccharidoses II by Sanger sequencing.
dc.identifier.urihttps://hdl.handle.net/20.500.14572/4184
dc.language.isoen_US
dc.publisherNepal Paediatric Society (JNPS)
dc.subjectBlueberry muffin lesions
dc.subjectiduronate 2-sulfatase
dc.subjectmissense mutation
dc.subjectMucopolysaccharidoses II (OMIM 309900)
dc.subjectfemale hunter syndrome
dc.titleAn Early Presentation of a Genomic Variant of Mucopolysaccharidoses II in a Female Newborn Baby
dc.typeArticle
dspace.entity.typePublication
local.article.typeCase Report
oaire.citation.endPage192
oaire.citation.startPage190
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relation.isJournalIssueOfPublication.latestForDiscoveryfc8cebda-778d-4d7f-b748-3a95706e9706
relation.isJournalOfPublication6f9be05c-05a9-4a3e-a5b5-a19a15ab042c

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